Evidence map›Paper›PMID 25116239›Full record

ArticlePloS one2014

Whole-genome sequencing of individuals from a founder population identifies candidate genes for asthma.

Catarina D Campbell, Kiana Mohajeri, Maika Malig, Fereydoun Hormozdiari, Benjamin Nelson, Gaixin Du, Kristen M Patterson, Celeste Eng, Dara G Torgerson, Donglei Hu and 23 more

Open access · goldAbstract read
In one paragraph

Article in PloS one, 2014. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 25 papers.

0numbers the graph read from it
0cells of the map it votes in
25citing papers in PubMed
2.6field-weighted citation impact, top 10% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

25 citing papers in PubMed, 37 citations in OpenAlex.

  1. Review
  2. Review
  3. Copy Number Variation in Asthma: An Integrative Review.Clinical reviews in allergy & immunology · 2025
    Review
  4. Asthma-Genomic Advances Toward Risk Prediction.Clinics in chest medicine · 2024
    Review
  5. Article
  6. Article
  7. Review
  8. Review
  9. Genetics and Epigenetics in Asthma.International journal of molecular sciences · 2021
    Review
  10. Article
  11. Article
  12. Pharmacogenetics of Pediatric Asthma: Current Perspectives.Pharmacogenomics and personalized medicine · 2020
    Review
  13. Article
  14. Article
  15. Review
  16. Article
  17. Article
  18. Whole-Genome Sequencing in Common Respiratory Diseases. Ready, Set, Go!American journal of respiratory and critical care medicine · 2017
    Article
  19. Article
  20. The puzzle of immune phenotypes of childhood asthma.Molecular and cellular pediatrics · 2016
    Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

33 authors at 8 institutions in 2 countries.

Catarina D CampbellDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Kiana MohajeriDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Maika MaligDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Fereydoun HormozdiariDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Benjamin NelsonDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Gaixin DuDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Kristen M PattersonDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Celeste EngDepartment of Medicine, University of California San Francisco, San Francisco, California, United States of America.
Dara G TorgersonDepartment of Medicine, University of California San Francisco, San Francisco, California, United States of America.
Donglei HuDepartment of Medicine, University of California San Francisco, San Francisco, California, United States of America.
Catherine HermanDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Jessica X ChongDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Arthur KoDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Brian J O'RoakDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Niklas KrummDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Laura VivesDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Choli LeeDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Lindsey A RothDepartment of Medicine, University of California San Francisco, San Francisco, California, United States of America.
William Rodriguez-CintronVeterans Caribbean Health Care System, San Juan, Puerto Rico, United States of America.
Jose Rodriguez-SantanaCentro de Neumología Pediátrica, San Juan, Puerto Rico, United States of America.
Emerita Brigino-BuenaventuraDepartment of Allergy & Immunology, Kaiser Permanente-Vallejo Medical Center, Vallejo, California, United States of America.
Adam DavisChildren's Hospital and Research Center Oakland, Oakland, California, United States of America.
Kelley MeadeChildren's Hospital and Research Center Oakland, Oakland, California, United States of America.
Michael A LeNoirBay Area Pediatrics, Oakland, California, United States of America.
Shannon ThyneSan Francisco General Hospital, San Francisco, California, and the Department of Pediatrics, University of California San Francisco, San Francisco, California, United States of America.
Daniel J JacksonDepartment of Pediatrics, University of Wisconsin, Madison, Wisconsin, United States of America.
James E GernDepartment of Pediatrics, University of Wisconsin, Madison, Wisconsin, United States of America.
Robert F LemanskeDepartment of Pediatrics, University of Wisconsin, Madison, Wisconsin, United States of America; Department of Medicine, University of Wisconsin, Madison, Wisconsin, United States of America.
Jay ShendureDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America.
Mark AbneyDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Esteban G BurchardDepartment of Medicine, University of California San Francisco, San Francisco, California, United States of America; Department of Bioengineering and Therapeutic Sciences, University of California San Francisco, San Francisco, California, United States of America.
Carole OberDepartment of Human Genetics, The University of Chicago, Chicago, Illinois, United States of America.
Evan E EichlerDepartment of Genome Sciences, University of Washington, Seattle, Washington, United States of America; Howard Hughes Medical Institute, Seattle, Washington, United States of America.
University of Washington · USUniversity of California, San Francisco · USUniversity of Chicago · USUniversity of Wisconsin–Madison · USCentro de Neumologia Pediatrica · PRKaiser Permanente Vallejo Medical Center · USKIPP Bay Area Schools · USVA Caribbean Healthcare System · PR

Funding

Understanding Asthma EndotypesU19AI077439 · NIAID · UNIVERSITY OF CALIFORNIA, SAN FRANCISCO · PI PRESCOTT G WOODRUFF · 2008 to 2026
$41.1M
Institutional Clinical and Translational Science AwardUL1TR000427 · NCATS · UNIVERSITY OF WISCONSIN-MADISON · PI DREZNER, MARC KENNETH · 2012 to 2016
$32.2M
Virus-Bacterial Interactions and Exacerba of AsthmaP01HL070831 · NHLBI · UNIVERSITY OF WISCONSIN-MADISON · PI LEMANSKE, ROBERT F · 2002 to 2017
$31.3M
University of Washington Medical Scientist Training Program: MD/PhDT32GM007266 · NIGMS · UNIVERSITY OF WASHINGTON · PI HORWITZ, MARSHALL S. · 1985 to 2023
$30.4M
New Approaches for Empowering Studies of Asthma in Populations of African DescentR01HL104608 · NHLBI · UNIVERSITY OF COLORADO DENVER · PI BARNES, KATHLEEN C, KENNY, EIMEAR ELIZABETH · 2011 to 2022
$23.1M
Re-Engineering Translational Research at the University of ChicagoUL1TR000430 · NCATS · UNIVERSITY OF CHICAGO · PI SOLWAY, JULIAN · 2012 to 2016
$20.2M
Regulation and expression of HLA-G in asthmatic airwaysU19AI095230 · NIAID · UNIVERSITY OF CHICAGO · PI KRISHNAN, JERRY A. · 2011 to 2016
$10.5M
Sex-Specific Genetic Architecture of Asthma-Associated Quantitative TraitsR01HL085197 · NHLBI · UNIVERSITY OF CHICAGO · PI OBER, CAROLE · 2007 to 2015
$7.6M
The EVE Asthma Genetics Consortium: Building Upon GWASRC2HL101651 · NHLBI · UNIVERSITY OF CHICAGO · PI NICOLAE, DAN LIVIU, OBER, CAROLE · 2009 to 2010
$7.4M
Social Interventions to address disparities In young adult tobacco useP60MD006902 · NIMHD · UNIVERSITY OF CALIFORNIA, SAN FRANCISCO · PI BIBBINS-DOMINGO, KIRSTEN · 2012 to 2016
$6.4M
Institutional Clinical and Translational Science AwardKL2TR000428 · NCATS · UNIVERSITY OF WISCONSIN-MADISON · PI DREZNER, MARC KENNETH · 2012 to 2016
$6.2M
Gene-environments and Admixture in Latino Asthmatics (GALA 2)R01ES015794 · NIEHS · UNIVERSITY OF CALIFORNIA, SAN FRANCISCO · PI BURCHARD, ESTEBAN GONZALEZ · 2008 to 2012
$5.4M
NCATS NIH HHS KL2 TR000428NCATS NIH HHS UL1 TR000427NCATS NIH HHS UL1TR000427NCATS NIH HHS UL1 TR000430NHGRI NIH HHS R01 HG002899NHLBI NIH HHS K23 HL004464NHLBI NIH HHS P01 HL070831NHLBI NIH HHS P01-HL070831NHLBI NIH HHS R01-HL004464NHLBI NIH HHS R01 HL078885NHLBI NIH HHS R01-HL078885NHLBI NIH HHS R01 HL085197NHLBI NIH HHS R01 HL088133NHLBI NIH HHS R01-HL088133NHLBI NIH HHS R01 HL104608NHLBI NIH HHS R01-HL104608NHLBI NIH HHS RC2 HL101651NIAID NIH HHS U19 AI077439NIAID NIH HHS U19-AI077439NIAID NIH HHS U19 AI095230NICHD NIH HHS R01 HD021244NICHD NIH HHS R01 HD21244NIEHS NIH HHS R01 ES015794NIEHS NIH HHS R01-ES015794NIGMS NIH HHS T32 GM007266NIMHD NIH HHS P60 MD006902NIMHD NIH HHS P60MD006902
6 · The paper itself

Abstract

Asthma is a complex genetic disease caused by a combination of genetic and environmental risk factors. We sought to test classes of genetic variants largely missed by genome-wide association studies (GWAS), including copy number variants (CNVs) and low-frequency variants, by performing whole-genome sequencing (WGS) on 16 individuals from asthma-enriched and asthma-depleted families. The samples were obtained from an extended 13-generation Hutterite pedigree with reduced genetic heterogeneity due to a small founding gene pool and reduced environmental heterogeneity as a result of a communal lifestyle. We sequenced each individual to an average depth of 13-fold, generated a comprehensive catalog of genetic variants, and tested the most severe mutations for association with asthma. We identified and validated 1960 CNVs, 19 nonsense or splice-site single nucleotide variants (SNVs), and 18 insertions or deletions that were out of frame. As follow-up, we performed targeted sequencing of 16 genes in 837 cases and 540 controls of Puerto Rican ancestry and found that controls carry a significantly higher burden of mutations in IL27RA (2.0% of controls; 0.23% of cases; nominal p = 0.004; Bonferroni p = 0.21). We also genotyped 593 CNVs in 1199 Hutterite individuals. We identified a nominally significant association (p = 0.03; Odds ratio (OR) = 3.13) between a 6 kbp deletion in an intron of NEDD4L and increased risk of asthma. We genotyped this deletion in an additional 4787 non-Hutterite individuals (nominal p = 0.056; OR = 1.69). NEDD4L is expressed in bronchial epithelial cells, and conditional knockout of this gene in the lung in mice leads to severe inflammation and mucus accumulation. Our study represents one of the early instances of applying WGS to complex disease with a large environmental component and demonstrates how WGS can identify risk variants, including CNVs and low-frequency variants, largely untested in GWAS.

Indexed as

Founder EffectGenetic Predisposition to DiseaseGenome, HumanGenome-Wide Association StudyAllelesAsthmaChromosome MappingComparative Genomic HybridizationDNA Copy Number VariationsEndosomal Sorting Complexes Required for TransportFemaleGene FrequencyGenetic VariationHigh-Throughput Nucleotide SequencingHumansIntronsEndosomal Sorting Complexes Required for TransportNedd4L protein, humanNedd4l protein, mouseNedd4 Ubiquitin Protein LigasesUbiquitin-Protein Ligases

Identifiers

PMID25116239
PMCPMC4130548
OpenAlexW2043820298

What Socratic holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.