Evidence map›Paper›PMID 26740943›Full record

ArticleMolecular genetics & genomic medicine2015

126 novel mutations in Italian patients with neurofibromatosis type 1.

Donatella Bianchessi, Sara Morosini, Veronica Saletti, Maria Cristina Ibba, Federica Natacci, Silvia Esposito, Claudia Cesaretti, Daria Riva, Gaetano Finocchiaro, Marica Eoli

Abstract read
In one paragraph

Article in Molecular genetics & genomic medicine, 2015. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 21 papers.

0numbers the graph read from it
0cells of the map it votes in
21citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

21 citing papers in PubMed.

  1. Article
  2. Article
  3. Article
  4. Biallelic variants in GTF3C3 result in an autosomal recessive disorder with intellectual disability.Genetics in medicine : official journal of the American College of Medical Genetics · 2025
    Article
  5. Expanding the phenotype of neurofibromatosis type 1 microdeletion syndrome.American journal of medical genetics. Part C, Seminars in medical genetics · 2024
    Article
  6. Review
  7. Article
  8. Review
  9. AtypicalGenes · 2021
    Review
  10. Evaluation of clinical findings and neurofibromatosis type 1 bright objects on brain magnetic resonance images of 60 Turkish patients with NF1 gene variants.Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology · 2021
    Article
  11. Article
  12. Article
  13. Article
  14. Article
  15. Article
  16. Article
  17. Review
  18. Article
  19. Article
  20. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors.

Donatella BianchessiMolecular Neuro-oncology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Sara MorosiniMolecular Neuro-oncology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Veronica SalettiDevelopmental Neurology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Maria Cristina IbbaMolecular Neuro-oncology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Federica NatacciMedical Genetics IRCSS Foundation, Cà Grande-Ospedale Maggiore Policlinico Milan Italy.
Silvia EspositoDevelopmental Neurology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Claudia CesarettiMedical Genetics IRCSS Foundation, Cà Grande-Ospedale Maggiore Policlinico Milan Italy.
Daria RivaDevelopmental Neurology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Gaetano FinocchiaroMolecular Neuro-oncology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.
Marica EoliMolecular Neuro-oncology IRCCS Foundation, "C. Besta" Neurological Institute Milan Italy.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Genetic analysis of Neurofibromatosis type 1 (NF1) may facilitate the identification of patients in early phases of the disease. Here, we present an overview of our diagnostic research spanning the last 11 years, with a focus on the description of 225 NF1 mutations, 126 of which are novel, found in a series of 607 patients (513 unrelated) in Italy. Between 2003 and 2013, 443 unrelated patients were profiled by denaturing high pressure liquid chromatography (DHPLC) analysis of 60 amplicons derived from genomic NF1 DNA and subsequent sequencing of heterozygotic PCR products. In addition, a subset of patients was studied by multiplex ligation-dependent probe amplification (MLPA) to identify any duplications, large deletions or microdeletions present at the locus. Over the last year, 70 unrelated patients were investigated by MLPA and sequencing of 22 amplicons spanning the entire NF1 cDNA. Mutations were found in 70% of the 293 patients studied by DHPLC, thereby fulfilling the NIH criterion for the clinical diagnosis of NF1 (detection rate: 70%); furthermore, 87% of the patients studied by RNA sequencing were genetically characterized. Mutations were also found in 36 of the 159 patients not fulfilling the NIH clinical criteria. We confirmed a higher incidence of intellectual disability in patients harboring microdeletion type 1 and observed a correlation between a mild phenotype and the small deletion c.2970_2972delAAT or the missense alteration in amino acid residue 1809 (p.Arg1809Cys). These data support the use of RNA-based methods for genetic analysis and provide novel information for improving the management of symptoms in oligosymptomatic patients.

Indexed as

Diagnostic criteriamutation databaseneurofibromatosis type 1 (NF1)novel mutations

Identifiers

PMID26740943
PMCPMC4694136

What Socratic holds

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.