Evidence mapPaperPMID 29502162Full record

Observational studyPediatric nephrology (Berlin, Germany)2018

Multimodal lipid-lowering treatment in pediatric patients with homozygous familial hypercholesterolemia-target attainment requires further increase of intensity.

Günter Klaus, Christina Taylan, Rainer Büscher, Claus Peter Schmitt, Lars Pape, Jun Oh, Joenna Driemeyer, Matthias Galiano, Jens König, Carsten Schürfeld and 5 more

Abstract readMulticenter StudyObservational Study
PubMed Publisher
In one paragraph

Observational study in Pediatric nephrology (Berlin, Germany), 2018. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 3 papers.

0numbers the graph read from it
0cells of the map it votes in
3citing papers in PubMed
1.9field-weighted citation impact, top 16% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

3 citing papers in PubMed, 14 citations in OpenAlex.

  1. Article
  2. An update on lipid apheresis for familial hypercholesterolemia.Pediatric nephrology (Berlin, Germany) · 2023
    Review
  3. Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

15 authors at 10 institutions in 1 country.

Günter KlausRenal Unit, KfH Pediatric Kidney Centre, and Centre for Undiagnosed and Rare Diseases, Marburg, Germany.
Christina TaylanPediatric Nephrology, Children's and Adolescents' Hospital, University Hospital of Cologne, Cologne, Germany.
Rainer BüscherPediatric Nephrology, Center for Pediatrics and Adolescent Medicine, Essen University Hospital, Essen, Germany.
Claus Peter SchmittPediatric Nephrology, University Hospital for Pediatric and Adolescent Medicine, Heidelberg, Germany.
Lars PapePediatric Nephrology, Center for Pediatrics and Adolescent Medicine and Dermatology, Hannover Medical School, Hannover, Germany.
Jun OhCenter for Obstetrics and Pediatrics, Department of Pediatrics, University Medical Center Hamburg-Eppendorf (UKE), Hamburg, Germany.
Joenna DriemeyerCenter for Obstetrics and Pediatrics, Department of Pediatrics, University Medical Center Hamburg-Eppendorf (UKE), Hamburg, Germany.
Matthias GalianoPediatric Nephrology, Center for Pediatrics and Adolescent Medicine, Erlangen University Hospital, Erlangen, Germany.
Jens KönigPediatric Nephrology, Center for Pediatrics and Adolescent Medicine, Münster University Hospital, Münster, Germany.
Carsten SchürfeldCenter for Nephrology and Dialysis, Saarlouis, Germany.
Ralf SpitthöverDialysis and Lipid Center North Rhine, Essen, Germany.
Juergen R SchaeferRenal Unit, KfH Pediatric Kidney Centre, and Centre for Undiagnosed and Rare Diseases, Marburg, Germany.
Lutz T WeberPediatric Nephrology, Children's and Adolescents' Hospital, University Hospital of Cologne, Cologne, Germany.
Andreas HeibgesApheresis Research Institute, Stadtwaldguertel 77, 50935, Cologne, Germany.
Reinhard KlingelApheresis Research Institute, Stadtwaldguertel 77, 50935, Cologne, Germany. klingel@apheresis-research.org.
Max Planck Institute for Metabolism Research · DEUniversity Hospital Cologne · DEUniversity Medical Center Hamburg-Eppendorf · DEEssen University Hospital · DEMedizinische Hochschule Hannover · DEPHV Dialysezentrum · DEUniversitätsklinikum Erlangen · DEUniversity Hospital Heidelberg · DEUniversity Hospital Münster · DEWest German Heart and Vascular Center Essen · DE

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

backgroundFamilial hypercholesterolemia (FH) causes premature cardiovascular disease (CVD). Lipoprotein apheresis (LA) is recommended as first-line lipid-lowering treatment (LLT) for homozygous (ho) FH.

methodsEfficacy of multimodal LLT including lifestyle counseling, drug treatment, and LA was analyzed in 17 pediatric hoFH or compound heterozygous (c-het) FH patients, who commenced chronic LA in Germany before the age of 18.

resultsAt time of diagnosis, mean low-density lipoprotein cholesterol (LDL-C) concentration was 19.6 mmol/l (756 mg/dl). Multimodal LLT resulted in 73% reduction of mean LDL-C concentration including a 62% contribution of LA. Only three children (18%) achieved mean LDL-C concentrations below the recommended pediatric target of 3.5 mmol/l (135 mg/dl). In 13 patients (76%) during chronic LA, neither cardiovascular events occurred nor was CVD progression detected clinically or by routine imaging techniques. In four patients (24%), cardiovascular events documented progression of CVD despite weekly LA, including one death due to coronary and cerebrovascular CVD which was not stabilized after commencing LA. Based on the mutational status, only 6 out of the 17 children were candidates for proprotein convertase subtilisin-kexin type 9 (PCSK9) inhibition. Two already responded with further LDL-C decrease by 40%.

conclusionsNext to drug therapy, regular LA is an essential component of LLT for approaching LDL-C targets in children with hoFH or c-hetFH, which was successful only in a minority of children. Progression of CVD morbidity and resulting mortality remain unresolved issues. Early and intensified multimodal LLT guided by risk factors beyond LDL-C concentration is needed to improve outcome.

Indexed as

AdolescentAnticholesteremic AgentsBlood Component RemovalCardiovascular DiseasesChildChild, PreschoolCholesterol, LDLCombined Modality TherapyCounselingFemaleGermanyHealthy LifestyleHeterozygoteHumansHyperlipoproteinemia Type IIMaleAnticholesteremic AgentsCholesterol, LDLLDLR protein, humanReceptors, LDLChildrenFamilial hypercholesterolemiaLDL-cholesterolLipoprotein apheresis preventionTreatment

Identifiers

PMID29502162
OpenAlexW2790360680

What Socratic holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.