Evidence mapPaperPMID 36715159Full record

ArticleHuman molecular genetics2023

Accelerated epigenetic aging and DNA methylation alterations in Berardinelli-Seip congenital lipodystrophy.

Abeer Qannan, Yosra Bejaoui, Mahmoud Izadi, Noha A Yousri, Aleem Razzaq, Colette Christiansen, George M Martin, Jordana T Bell, Steve Horvath, Junko Oshima and 4 more

Open access · hybridAbstract read
In one paragraph

Article in Human molecular genetics, 2023. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 7 papers.

0numbers the graph read from it
0cells of the map it votes in
7citing papers in PubMed
3.4field-weighted citation impact, top 7% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

7 citing papers in PubMed, 16 citations in OpenAlex.

  1. Review
  2. Article
  3. Article
  4. Article
  5. The impact of COVID-19 on "biological aging".Frontiers in immunology · 2024
    Review
  6. Article
  7. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

14 authors at 7 institutions in 7 countries.

Abeer QannanCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Yosra BejaouiCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Mahmoud IzadiCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Noha A YousriGenetic Medicine, Weill Cornell Medicine-Qatar, Doha, Qatar.
Aleem RazzaqCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Colette ChristiansenDepartment of Twin Research and Genetic Epidemiology, King's College London, London, UK.ORCID 0000-0001-6034-5746
George M MartinDepartment of Laboratory Medicine and Pathology, University of Washington, Seattle, WA 98105, USA.
Jordana T BellDepartment of Twin Research and Genetic Epidemiology, King's College London, London, UK.
Steve HorvathAltos Labs, San Diego, USA.
Junko OshimaDepartment of Laboratory Medicine and Pathology, University of Washington, Seattle, WA 98105, USA.
Andre MegarbaneDepartment of Human Genetics, Gilbert and Rose-Marie Chagoury School of Medicine, Lebanese American University, Byblos, Lebanon.ORCID 0000-0003-0714-2469
Johan EricssonCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Ehsan PourkarimiCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.
Nady El HajjCollege of Health and Life Sciences, Hamad Bin Khalifa University, Qatar Foundation, Doha 34110, Qatar.ORCID 0000-0003-3420-8531
Hamad bin Khalifa University · QAKing's College London · GBChiba University · JPFondation Jérôme-Lejeune · FRUniversity of California, Los Angeles · USUniversity of Washington · USWeill Cornell Medical College in Qatar · QA

Funding

International Registry for Werner SyndromeR01CA210916 · NCI · UNIVERSITY OF WASHINGTON · 2023 to 2025
$736k
Enhancing and expanding the CGC Strain CollectionP40OD010440 · UNIVERSITY OF MINNESOTA · 2025 to 2025
$455k
NCI NIH HHS R01 CA210916NIH HHS P40 OD010440
6 · The paper itself

Abstract

Berardinelli-Seip congenital lipodystrophy type 2 (CGL2) is a very rare human genetic disorder with potential significance to the understanding of the pathobiology of aging. CGL2 patients display characteristic progeroid features and suffer from type 2 diabetes, insulin resistance and fatty liver. In this study, we profiled genome-wide DNA methylation levels in CGL2 patients with BSCL2 mutations to study epigenetic age acceleration and DNA methylation alterations. This analysis revealed significant age acceleration in blood DNA of CGL2 patients using both first- and second-generation epigenetic clocks. We also observed a shortened lifespan of Caenorhabditis elegans following knockdown of the BSCL2 homolog seip-1 on a daf-16/forkhead box, class O mutant background. DNA methylation analysis revealed significant differentially methylated sites enriched for lyase activity, kinase regulator activity, protein kinase regulator activity and kinase activator activity. We could also observe significant hypomethylation in the promoter of the dual specificity phosphatase 22 gene when comparing CGL2 patients versus controls. We conclude that in line with the observed progeroid features, CGL2 patients exhibit significant epigenetic age acceleration and DNA methylation alterations that might affect pathways/genes of potential relevance to the disease.

Indexed as

Diabetes Mellitus, Type 2GTP-Binding Protein gamma SubunitsLipodystrophyLipodystrophy, Congenital GeneralizedAgingDNA MethylationEpigenesis, GeneticHumansMutationGTP-Binding Protein gamma Subunits

Identifiers

PMID36715159
PMCPMC10196674
OpenAlexW4318478178

What Socratic holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.