Evidence mapPaperPMID 37589388Full record

ReviewNeuro-oncology2024

A review of current therapeutics targeting the mitochondrial protease ClpP in diffuse midline glioma, H3 K27-altered.

Evangeline R Jackson, Mika L Persson, Cameron J Fish, Izac J Findlay, Sabine Mueller, Javad Nazarian, Esther Hulleman, Jasper van der Lugt, Ryan J Duchatel, Matthew D Dun

Open access · hybridAbstract readReview
In one paragraph

Review in Neuro-oncology, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 21 papers, 1 of them a synthesis that pooled it.

0numbers the graph read from it
0cells of the map it votes in
21citing papers in PubMed, 1 pooled it
8.3field-weighted citation impact, top 2% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

21 citing papers in PubMed, 1 synthesis or guideline pooled it, 29 citations in OpenAlex.

  1. Pooled it
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  13. Case Report: Application ofFrontiers in oncology · 2025
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4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors at 4 institutions in 4 countries.

Evangeline R JacksonCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.ORCID 0000-0002-2245-9213
Mika L PerssonCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.ORCID 0000-0001-8967-7242
Cameron J FishCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.
Izac J FindlayCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.ORCID 0000-0002-3192-5888
Sabine MuellerDIPG/DMG Center Zurich, University Children's Hospital Zürich, Zurich, Switzerland.
Javad NazarianDIPG/DMG Center Zurich, University Children's Hospital Zürich, Zurich, Switzerland.ORCID 0000-0002-1951-9828
Esther HullemanPrincess Máxima Center for Pediatric Oncology, Utrecht, Netherlands, Utrecht, Netherlands.
Jasper van der LugtPrincess Máxima Center for Pediatric Oncology, Utrecht, Netherlands, Utrecht, Netherlands.
Ryan J DuchatelCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.ORCID 0000-0002-3651-7672
Matthew D DunCancer Signalling Research Group, School of Biomedical Sciences and Pharmacy, College of Health, Medicine and Wellbeing, University of Newcastle, Callaghan, New South Wales, Australia.ORCID 0000-0002-9063-5370
Hunter Medical Research Institute · AUPrincess Máxima Center · NLChildren's National · USUniversity of California, San Francisco · US

Funding

Aidan's AvengersAmerican Childhood Cancer OrganizationAubreigh's ArmyAustin StrongAustralian Communities FoundationAustralian Lions Childhood Cancer Research FoundationBenny's WorldBlackjack FoundationBrooke Healey FoundationCancer Institute NSW FellowshipChadTough Defeat DIPG New InvestigatorChadTough FoundationCharlie Teo FoundationCure Brain CancerCureCell ExCELLerateDIPGEdie's Kindness ProjectEvie Poolman Research GiftGabriella's Smile FoundationHunter Cancer Research AllianceHunter Medical Research InstituteIsabella and Marcus FoundationJeffrey Thomas Hayden FoundationJosephine Dun ScholarshipJulia Barbara FoundationKinghorn FoundationKiriwina InvestmentsLauren's Fight for CureLaurie's Love FoundationLily Larue FoundationLittle Legs FoundationLiv Like a UnicornLove Chloe FoundationMaitland Cancer Appeal LimitedMcDonald Jones FoundationMiette Skiller Scholarship FundMusella FoundationNHMRC GNT1173892Pacific Pediatric Neuro-Oncology Consortium FoundationPray Hope BelieveReflections of GraceRobert Connor Dawes FoundationRUN DIPGRyan's HopeStorm the Heavens FundThe Cure Starts Now FoundationThe Cure Starts Now Foundation AustraliaThe Gold Hope ProjectThe Kids' Cancer ProjectTour De CureVINVAGroupWayland Villars FoundationWhitley's WishesYuvaan Tiwari Foundation
6 · The paper itself

Abstract

Diffuse midline gliomas (DMGs) are devastating pediatric brain tumors recognized as the leading cause of cancer-related death in children. DMGs are high-grade gliomas (HGGs) diagnosed along the brain's midline. Euchromatin is the hallmark feature of DMG, caused by global hypomethylation of H3K27 either through point mutations in histone H3 genes (H3K27M), or by overexpression of the enhancer of zeste homolog inhibitory protein. In a clinical trial for adults with progressive HGGs, a 22-year-old patient with a thalamic DMG, H3 K27-altered, showed a remarkable clinical and radiological response to dordaviprone (ONC201). This response in an H3 K27-altered HGG patient, coupled with the lack of response of patients harboring wildtype-H3 tumors, has increased the clinical interest in dordaviprone for the treatment of DMG. Additional reports of clinical benefit have emerged, but research defining mechanisms of action (MOA) fall behind dordaviprone's clinical use, with biomarkers of response unresolved. Here, we summarize dordaviprone's safety, interrogate its preclinical MOA identifying the mitochondrial protease "ClpP" as a biomarker of response, and discuss other ClpP agonists, expanding the arsenal of potential weapons in the fight against DMG. Finally, we discuss combination strategies including ClpP agonists, and their immunomodulatory effects suggestive of a role for the tumor microenvironment in DMG patient response.

Indexed as

Antineoplastic AgentsBrain NeoplasmsEndopeptidase ClpGliomaAnimalsHistonesHumansMitochondriaAntineoplastic AgentsClpP protein, humanEndopeptidase ClpHistonesCLPPCLPP agonistDMGdordaviproneONC201

Identifiers

PMID37589388
PMCPMC11066926
OpenAlexW4385898176

What Socratic holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.