Evidence mapPaperPMID 37628281Full record

ArticleChildren (Basel, Switzerland)2023

Clinical Characterization of Pediatric Erythromelalgia: A Single-Center Case Series.

Jenny Sun, Don Daniel Ocay, Meghan Halpin, Kimberly Lobo, Dafni F T Frohman, Carolina Donado, Catherine A Brownstein, Casie A Genetti, Anna Madden, Charles B Berde

Abstract read
In one paragraph

Article in Children (Basel, Switzerland), 2023. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

0numbers the graph read from it
0cells of the map it votes in
2citing papers in PubMed
field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

2 citing papers in PubMed.

  1. Article
  2. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors.

Jenny SunDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.ORCID 0009-0003-5209-2170
Don Daniel OcayDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.
Meghan HalpinDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.ORCID 0000-0002-7589-071X
Kimberly LoboDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.
Dafni F T FrohmanDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.
Carolina DonadoDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.
Catherine A BrownsteinManton Center for Orphan Disease Research, Division of Genetics and Genomics, Boston Children's Hospital, Boston, MA 02115, USA.ORCID 0000-0002-7371-0340
Casie A GenettiManton Center for Orphan Disease Research, Division of Genetics and Genomics, Boston Children's Hospital, Boston, MA 02115, USA.
Anna MaddenManton Center for Orphan Disease Research, Division of Genetics and Genomics, Boston Children's Hospital, Boston, MA 02115, USA.ORCID 0009-0006-7735-8854
Charles B BerdeDepartment of Anesthesiology, Critical Care, and Pain Medicine, Boston Children's Hospital, Boston, MA 02115, USA.

Funding

Boston Children's Hospital Children's Rare Disease Cohorts Initiative N/ASara Page Mayo Endowment for Pediatric Pain Research N/A
6 · The paper itself

Abstract

Erythromelalgia is a descriptive term for severe burning pain and erythema in the distal extremities relieved by cold and exacerbated by heat. Pediatric case series to date are relatively small. We extracted and analyzed medical record data for 42 pediatric patients to describe clinical characteristics, associated conditions, and responses to treatments. Informed consent was obtained according to an IRB-approved protocol that included gene discovery. Three patients had confirmed Nav1.7 sodium channelopathies, with six additional patients under investigation with novel gene candidates. There was a female predominance (2.5:1), and the median onset age was 12 years (IQR = 3-14). Patients saw a median of three specialists (IQR = 2-3) for a diagnosis. The majority (90%) reported bilateral symptoms. Cooling methods usually provided partial relief, while heat and exercise exacerbated pain. No medication appeared to be consistently effective; commonly prescribed medications included sodium channel blockers (

Indexed as

erythromelalgiasmall-fiber neuropathysodium channelopathy

Identifiers

PMID37628281
PMCPMC10453121

What Socratic holds

Textmetadata
LicenceCC BY
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Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.