Evidence map›Paper›PMID 39017781›Full record

ReviewImmunologic research2024

A novel MALT1 variant in an Egyptian patient presenting with exfoliative dermatitis: a case-based review.

Rabab El Hawary, Safa Meshaal, Sohilla Lotfy, Dalia Abd Elaziz, Alia S Eldash, Aya Erfan, Radwa Alkady, Rania Darwish, Mai Saad, Engy Chohayeb and 2 more

Abstract readCase ReportsReview
PubMed Publisher
In one paragraph

Review in Immunologic research, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

12 authors.

Rabab El HawaryDepartment of Clinical and Chemical Pathology, Faculty of Medicine, Cairo University, Cairo, 11562, Egypt. rabab.elhawary@kasralainy.edu.eg.
Safa MeshaalDepartment of Clinical and Chemical Pathology, Faculty of Medicine, Cairo University, Cairo, 11562, Egypt.
Sohilla LotfyDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Dalia Abd ElazizDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Alia S EldashDepartment of Clinical and Chemical Pathology, Faculty of Medicine, Cairo University, Cairo, 11562, Egypt.
Aya ErfanDepartment of Clinical and Chemical Pathology, Faculty of Medicine, Cairo University, Cairo, 11562, Egypt.
Radwa AlkadyDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Rania DarwishDepartment of Clinical and Chemical Pathology, Faculty of Medicine, Cairo University, Cairo, 11562, Egypt.
Mai SaadDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Engy ChohayebDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Nermeen GalalDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.
Aisha M ElmarsafyDepartment of Pediatrics, Faculty of Medicine, Cairo University, Cairo, Egypt.

Funding

Science, Technology & Innovation Funding Authority (STDF) 38174
6 · The paper itself

Abstract

Inborn errors of the CARD11-BCL10-MALT1 (CBM) signalosome have recently been shown to underlie severe combined immunodeficiency (SCID) and combined immunodeficiency (CID) with variable immunological and clinical phenotypes, and patients usually present with recurrent bacterial, viral, and fungal infections, periodontal disease, enteropathy, dermatitis, and failure to thrive. In the present study, we describe the clinical and immunological characteristics of an Egyptian patient with a mutation in the MALT1 gene. The patient suffered from an itchy exfoliative skin rash and eczematous lesions over his face and flexural surface of the limbs. He also had dental enamel erosion, repeated attacks of diarrhea, and pneumonia. He had elevated serum IgE and normal B- and T-lymphocyte subset counts, but there was an arrest in the B-cell maturation. DOCK8 expression on the lymphocytes by flow cytometry was normal. Next-generation sequencing revealed a novel homozygous variant in the MALT1 gene (c.762dup in exon 5 of 17; p.Ile255TyrfsTer10); this variant is likely pathogenic, thus supporting the genetic diagnosis of immunodeficiency-12 (IMD12). Although the presence of eczema, recurrent sinopulmonary, and staphylococcal infections are suggestive of DOCK8 deficiency, they are also a finding in CARD11 and MALT1 deficiency. Thus, whenever DOCK 8 has been excluded, the molecular diagnosis is mandatory as this could lead to discovering more patients hence better understanding and reporting of the phenotype and natural history of the disease especially since there are very few documented cases. Early diagnosis will also enable the proper patient management by hematopoietic stem cell transplantation (HSCT) prior to the establishment of infections and pulmonary damage leading to a better outcome.

Indexed as

Dermatitis, ExfoliativeMucosa-Associated Lymphoid Tissue Lymphoma Translocation 1 ProteinEgyptHumansMaleMutationMALT1 protein, humanMucosa-Associated Lymphoid Tissue Lymphoma Translocation 1 ProteinCombined immunodeficiencyEczemaMALT1next-generation sequencing

Identifiers

What Socratic holds

Textmetadata
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Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.