Evidence map›Paper›PMID 39709514›Full record

ArticleJournal of medical case reports2024

Abdominal kaposiform hemangioendothelioma presenting as volvulus and recurring intestinal obstruction in a neonate: a case report.

Salaar Ahmed, Bakhtawar Dilawar, Sarosh Moeen, Shahzadi Dilawar, Hafsa Sheikh, Muhammad Anwar Arain

Abstract readCase Reports
In one paragraph

Article in Journal of medical case reports, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

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0cells of the map it votes in
2citing papers in PubMed
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1 · What the graph read from it

What it found

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2 · The registry

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3 · Its place in the literature

Who cites it

2 citing papers in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

6 authors.

Salaar Ahmed *Medical College, Aga Khan University, Stadium Road, Karachi, 74800, Pakistan. salaar.ahmed@scholar.aku.edu.ORCID http://orcid.org/0000-0002-0834-5535
Bakhtawar Dilawar *Department of Surgery, Aga Khan University, Karachi, Pakistan.
Sarosh MoeenDepartment of Pathology, Aga Khan University, Karachi, Pakistan.
Shahzadi DilawarNational Institute of Child Health, Karachi, Pakistan.
Hafsa SheikhDepartment of Surgery, Aga Khan University, Karachi, Pakistan.
Muhammad Anwar ArainDepartment of Surgery, Aga Khan University, Karachi, Pakistan.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

backgroundKaposiform hemangioendothelioma is a rare vascular tumor primarily occurring in infants and children. The most common sites for kaposiform hemangioendothelioma are extremities, with very few cases of abdominal kaposiform hemangioendothelioma reported in neonates. Making a diagnosis of Kaposiform hemangioendothelioma can be challenging when the patient presents with generalized symptoms such as bilious vomiting and constipation that can be attributed to other more common causes of intestinal obstruction. CASE PRESENTATION: A 28-day-old Pakistani baby girl presented with bilious vomiting and constipation. The abdomen was distended, and scans showed generalized dilation of bowel loops. A preliminary diagnosis of intestinal obstruction due to volvulus was made, and the patient underwent an exploratory laparotomy. Postoperatively, the patient remained unwell with profuse aspirates in nasogastric and no improvement in ileus. Repeat scans were again suggestive of midgut volvulus, which was initially managed conservatively, but later redo surgery was done. Ischemic bowel was resected with histopathology showing kaposiform hemangioendothelioma. In the meantime, the baby developed an abdominal collection, infection, and short gut syndrome due to resection of the bowel. The family was counseled regarding the prognosis, and the patient was transferred from hospital to home upon request. The baby passed away 2 days later.

conclusionWhile extremely rare, abdominal kaposiform hemangioendothelioma can be an important and potentially lifesaving differential diagnosis to consider in neonates and infants with recurring and nonresolving intestinal obstruction. The management is complex, and prognosis can be poor in diffuse, congested lesions involving a large part of the gut.

Indexed as

HemangioendotheliomaIntestinal ObstructionIntestinal VolvulusKasabach-Merritt SyndromeSarcoma, KaposiDiagnosis, DifferentialFemaleHumansInfant, NewbornLaparotomyRecurrenceBowel obstructionKaposiform hemangioendotheliomaNeonatePediatric surgeryVolvulus

Identifiers

PMID39709514
PMCPMC11663361

What Socratic holds

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LicenceCC BY-NC-ND
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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.