Anesthetic management in pregnancy with osteogenesis imperfecta type XI: A comprehensive case report.

Korakod Punnaniti, Lisa Sangkum, Sivaporn Termpornlert, Rojnarin Komonhirun, Sasima Dusitkasem

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Article in International journal of surgery case reports, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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5 authors.

Korakod PunnanitiDepartment of Anesthesiology, Faculty of Medicine Ramathibodi Hospital, Mahidol University, Bangkok, Thailand.

Lisa SangkumDepartment of Anesthesiology, Faculty of Medicine Ramathibodi Hospital, Mahidol University, Bangkok, Thailand.

Sivaporn TermpornlertDepartment of Anesthesiology, Faculty of Medicine Ramathibodi Hospital, Mahidol University, Bangkok, Thailand.

Rojnarin KomonhirunDepartment of Anesthesiology, Faculty of Medicine Ramathibodi Hospital, Mahidol University, Bangkok, Thailand.

Sasima DusitkasemDepartment of Anesthesiology, Faculty of Medicine Ramathibodi Hospital, Mahidol University, Bangkok, Thailand. Electronic address: sasima1308@gmail.com.

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6 · The paper itself

Abstract

introductionOsteogenesis imperfecta (OI) type XI or Bruck syndrome is an extremely rare genetic disorder characterized by congenital joint contractures and bone fragility. OI presents unique and considerable challenges in the perioperative and anesthetic management of affected patients. PRESENTATION OF CASE: A 29-year-old primigravida with OI type XI (100 cm, 26 kg) and severe kyphoscoliosis underwent urgent Caesarean delivery at 32 weeks under general anesthesia (sevoflurane/nitrous oxide). A female infant (1470 g) required resuscitation. Postoperative recovery was uneventful. DISCUSSION: The rarity of this syndrome, along with the physiological changes associated with pregnancy, creates an unprecedented clinical scenario that demands a thorough and cautious approach to patient care.

conclusionOsteogenesis imperfecta (OI) type XI necessitates careful anesthetic management in pregnancy. This case highlights the anesthetic management challenges and the use of a multidisciplinary approach to enhance clinical understanding and improve patient outcomes.

Indexed as

Bruck syndromeCaesarean deliveryFKBP10 mutationGeneral anesthesiaOsteogenesis imperfecta (OI) type XI

Identifiers

PMID39893961

DOI10.1016/j.ijscr.2025.110971

PMCPMC11836480

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