Evidence map›Paper›PMID 40463491›Full record

ArticlePulmonary circulation2025

Juvenile Systemic Sclerosis Presenting With Severe Pulmonary Vascular Disease: ECMO Stabilization During Aggressive Therapy Resulting in a Favorable Outcome.

Stephanie M Tsoi, Shannon Cheung, Roberto Alejandro Valdovinos, Elena Amin, Hythem Nawaytou, Elizabeth Colglazier, Claire Parker, April Edwell, Susan Kim, Jeffrey R Fineman

Abstract read
In one paragraph

Article in Pulmonary circulation, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors.

Stephanie M TsoiDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.ORCID https://orcid.org/0000-0002-0115-5843
Shannon CheungDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.
Roberto Alejandro ValdovinosDivision of Rheumatology, Department of Pediatrics University of California, San Francisco San Francisco California USA.
Elena AminDivision of Cardiology, Department of Pediatrics University of California San Francisco San Francisco California USA.
Hythem NawaytouDivision of Cardiology, Department of Pediatrics University of California San Francisco San Francisco California USA.
Elizabeth ColglazierDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.
Claire ParkerDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.ORCID https://orcid.org/0000-0002-8431-7130
April EdwellDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.
Susan KimDivision of Rheumatology, Department of Pediatrics University of California, San Francisco San Francisco California USA.
Jeffrey R FinemanDivision of Critical Care Medicine, Department of Pediatrics University of California San Francisco San Francisco California USA.ORCID https://orcid.org/0000-0001-9740-405X

Funding

TGF-ß-SOX18-Collagen metabolism in pulmonary vascular disease associated with CHDP01HL146369 · NHLBI · UNIVERSITY OF ARIZONA · PI JEFFREY R FINEMAN · 2020 to 2026
$18.7M
Multidisciplinary Research Training in Pediatric Pulmonary Vascular DiseaseT32HL160508 · NHLBI · UNIVERSITY OF CALIFORNIA, SAN FRANCISCO · PI Steven Herbert Abman, Eric Douglas Austin · 2022 to 2026
$1.7M
NHLBI NIH HHS P01 HL146369NHLBI NIH HHS T32 HL160508
6 · The paper itself

Abstract

Juvenile systemic sclerosis (jSSc) associated pulmonary hypertension (PH) is rare, but, the leading cause of morbidity and mortality in jSSc. This is a case of a 10-year-old girl whose initial presentation of positive U3-RNP antibody jSSc included diffuse skin findings, severe pulmonary arterial hypertension, and right ventricular failure. Veno-arterial extracorporeal membranous oxygenation (VA-ECMO) and atrial stent placement facilitated treatment with pulse-dose steroids, mycophenolate mofetil, and B-cell depleting therapy to treat the underlying autoimmune inflammation and triple therapy with treprostinil, ambrisentan, and tadalafil for her pulmonary hypertension. At 9-month follow-up, her jSSc is well-controlled with complete resolution of her PH. This case demonstrates that multi-disciplinary treatment, including upfront multi-drug therapy for jSSC and PAH, that included VA-ECMO, may improve outcomes, particularly when treatment for underlying causes (in this case, jSSc) is just being initiated.

Indexed as

extracorporeal membranous oxygenationjuvenile systemic sclerosispediatric critical carepulmonary hypertensionright ventricular failure

Identifiers

PMID40463491
PMCPMC12130638

What Socratic holds

Textmetadata
LicenceCC BY-NC
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.