Evidence map›Paper›PMID 40525640›Full record

ArticleAdvanced science (Weinheim, Baden-Wurttemberg, Germany)2025

The Non-Coding Regulatory Variant rs2863002 at chr11p11.2 Increases Neuroblastoma Risk by Affecting HSD17B12 Expression and Lipid Metabolism.

Teresa Maiorino, Marianna Avitabile, Vincenzo Aievola, Annalaura Montella, Vito A Lasorsa, Ferdinando Bonfiglio, Mariagrazia Cantalupo, Sueva Cantalupo, Gilda Estinto, Matilde Tirelli and 11 more

Abstract read
In one paragraph

Article in Advanced science (Weinheim, Baden-Wurttemberg, Germany), 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 3 papers.

0numbers the graph read from it
0cells of the map it votes in
3citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

3 citing papers in PubMed.

  1. Article
  2. Article
  3. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

21 authors.

Teresa MaiorinoDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.ORCID https://orcid.org/0000-0003-3005-7836
Marianna AvitabileDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Vincenzo AievolaDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Annalaura MontellaDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Vito A LasorsaCEINGE Biotecnologie Avanzate Franco Salvatore, Naples, 80145, Italy.
Ferdinando BonfiglioDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Mariagrazia CantalupoDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Sueva CantalupoDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Gilda EstintoCEINGE Biotecnologie Avanzate Franco Salvatore, Naples, 80145, Italy.
Matilde TirelliDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Martina MoriniLaboratory of Experimental Therapies in Oncology, IRCCS Istituto Giannina Gaslini, Genoa, 16147, Italy.
Martina ArditoLaboratory of Experimental Therapies in Oncology, IRCCS Istituto Giannina Gaslini, Genoa, 16147, Italy.
Alessandra EvaScientific Directorate, IRCCS Istituto Giannina Gaslini, Genoa, 16147, Italy.
Vincenza CerboneCEINGE Biotecnologie Avanzate Franco Salvatore, Naples, 80145, Italy.
Lucia MaurielloCEINGE Biotecnologie Avanzate Franco Salvatore, Naples, 80145, Italy.
Marianna CaterinoDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Margherita RuoppoloDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
John M MarisThe Children's Hospital of Philadelphia and the Department of Pediatrics, Perelman School of Medicine, University of Pennsylvania, Philadelphia, PA, 19104, USA.
Sharon J DiskinThe Children's Hospital of Philadelphia and the Department of Pediatrics, Perelman School of Medicine, University of Pennsylvania, Philadelphia, PA, 19104, USA.
Achille IolasconDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.
Mario CapassoDepartment of Molecular Medicine and Medical Biotechnology at University of Naples "Federico II", Naples, 80131, Italy.ORCID https://orcid.org/0000-0003-3306-1259

Funding

Discovering mechanisms of neuroblastoma tumorigenesis to improve patient outcomesR35CA220500 · NCI · CHILDREN'S HOSP OF PHILADELPHIA · PI JOHN M MARIS · 2017 to 2026
$8.7M
The Genetic Basis of Neuroblastoma TumorigenesisR01CA124709 · NCI · CHILDREN'S HOSP OF PHILADELPHIA · PI MARIS, JOHN M · 2008 to 2017
$6.3M
Elucidating the role of the noncoding genome in neuroblastomaR01CA237562 · NCI · CHILDREN'S HOSP OF PHILADELPHIA · PI DISKIN, SHARON · 2021 to 2025
$2.0M
Associazione Italiana per la Ricerca sul Cancro 25 796Fondazione Italiana per la Lotta al NeuroblastomaItalian Ministry for University and Research (MUR) National Recovery and Resilience Plan (PNRR) CUP-E53D23015470001Italian Ministry for University and Research (MUR) National Recovery and Resilience Plan (PNRR) PRIN P2022NFCPMNCI NIH HHS R01 CA124709NCI NIH HHS R01 CA237562NCI NIH HHS R35 CA220500NIH HHS R01-CA237562NIH HHS R35-CA124709NIH HHS R35-CA220500OPEN Associazione Oncologia Pediatrica e Neuroblastoma ONLUS
6 · The paper itself

Abstract

A Genome-wide association study (GWAS) on a European-American cohort identified chr11p11.2 as a neuroblastoma predisposition locus. Combining in-house and public genomic data from neuroblastoma cell lines, this work implicates rs2863002 as the candidate causal variant at the 11p11.2 locus, confirming its cis-regulatory activity through a luciferase reporter assay. The genetic association of rs2863002 with neuroblastoma risk is validated in an Italian case-control cohort. Using ChIP-qPCR, Hi-C, and CRISPR genome editing, this work deciphers the regulatory mechanisms at the risk locus, demonstrating that the rs2863002-C risk allele regulates HSD17B12 expression and reduces GATA3 binding affinity. In vitro functional assays and targeted lipidomic analyses reveal the involvement of the rs2863002-C risk allele in tumorigenicity and modulation of lipid metabolism in neuroblastoma cells through HSD17B12 regulation. This study provides new insights into the genetic basis of neuroblastoma and underscores the importance of post-GWAS functional characterization of risk loci in uncovering relevant biological findings for understanding complex diseases.

Indexed as

17-Hydroxysteroid DehydrogenasesGenetic Predisposition to DiseaseLipid MetabolismNeuroblastomaAllelesCase-Control StudiesCell Line, TumorGenome-Wide Association StudyHumansPolymorphism, Single Nucleotide17-Hydroxysteroid Dehydrogenasesfunctional genomicsgenetic predispositionGWASHSD17B12lipid metabolismneuroblastomaSNP

Identifiers

PMID40525640
PMCPMC12412506

What Socratic holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.