Evidence map›Paper›PMID 40741157›Full record

ArticleRadiology case reports2025

A case of Axenfeld-Rieger syndrome with neuroradiological abnormalities.

Yu Ohkubo, Takaki Hayashi, Kohmei Ida, Eiji Nakano, Akiyoshi Hamada, Tomohiko Higashida, Yasumasa Asakawa, Kohki Yoshikawa, Tokuzo Yokokawa, Masao Tago

Abstract readCase Reports
In one paragraph

Article in Radiology case reports, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors.

Yu OhkuboDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Takaki HayashiDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Kohmei IdaDepartment of Pediatrics, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Eiji NakanoDepartment of Pediatrics, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Akiyoshi HamadaDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Tomohiko HigashidaDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Yasumasa AsakawaDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Kohki YoshikawaDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Tokuzo YokokawaDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.
Masao TagoDepartment of Radiology, Teikyo University Mizonokuchi Hospital, Kawasaki, Japan.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Axenfeld-Rieger syndrome is a rare autosomal dominant disorder characterized primarily by developmental anomalies of the anterior segment of the eye and systemic manifestations, including craniofacial abnormalities, dental anomalies, and neurological involvement. Although genetic mutations in the forkhead box C1 (FOXC1) or paired-like homeodomain transcription factor 2 (PITX2) have been implicated, the full extent of associated neurological features remains underexplored. We present the case of a 2-year-old boy diagnosed with Axenfeld-Rieger syndrome who exhibited mild facial dysmorphism and required surgical intervention for glaucoma. Genetic testing identified a FOXC1 mutation, and family history revealed that his father and paternal grandfather were also affected. Brain magnetic resonance imaging scans revealed periventricular white matter lesions, dilated perivascular spaces, and vertebrobasilar artery dolichoectasia. This case underscores the potential for significant neurological findings in patients with Axenfeld-Rieger syndrome and highlights the clinical value of comprehensive neuroradiological evaluation in such cases.

Indexed as

Axenfeld–Rieger syndromeCerebral small vascular diseaseChromosome 6p25FOXC1White matter lesion

Identifiers

PMID40741157
PMCPMC12310057

What Socratic holds

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.