Evidence map›Paper›PMID 40756852›Full record

ArticleJournal of the Royal Society of New Zealand2025

Genetic diagnostic outcomes from a 10-year research programme in autism in Aotearoa New Zealand.

Suzanne M Musgrave, Juliet Taylor, Whitney Whitford, Alexandra Garton, Jessie Poquérusse, Victoria Hawkins, Waiora Port, Kriebashne S Moodley, Ruth Monk, Sarah D Knowles and 12 more

Abstract read
In one paragraph

Article in Journal of the Royal Society of New Zealand, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

22 authors.

Suzanne M MusgraveSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0009-0003-6006-281X
Juliet TaylorGenetic Health Service New Zealand, Auckland City Hospital, Auckland, New Zealand.
Whitney WhitfordSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0001-7833-1502
Alexandra GartonSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-1833-0388
Jessie PoquérusseSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0003-0640-229X
Victoria HawkinsSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-1376-9682
Waiora PortCentre for Brain Research, The University of Auckland, Auckland, New Zealand.
Kriebashne S MoodleySchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.
Ruth MonkDepartment of Anatomy and Medical Imaging, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-7776-942X
Sarah D KnowlesCentre for Longitudinal Research - He Ara ki Mua, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-2352-9754
Caroline WalkerCentre for Longitudinal Research - He Ara ki Mua, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-9210-7651
Christopher SamsonSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0001-6543-6209
Lydia VelzianSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0003-0979-3695
Brendan SwanSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.
Donald R LoveDiagnostic Genetics, LabPLUS, Auckland City Hospital, Auckland, New Zealand.ORCID https://orcid.org/0000-0003-4669-8769
Rosamund HillDepartment of Neurology, Auckland City Hospital, Auckland, New Zealand.
Colette MuirDevelopmental Paediatrics Starship, Auckland City Hospital, Auckland, New Zealand.
Michael E TalkowskiProgram in Medical and Population Genetics, Broad Institute of MIT and Harvard, Cambridge, MA, USA.ORCID https://orcid.org/0000-0003-2889-0992
Chelsea LowtherProgram in Medical and Population Genetics, Broad Institute of MIT and Harvard, Cambridge, MA, USA.ORCID https://orcid.org/0000-0001-6723-1899
Russell G SnellSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0002-8166-4014
Klaus LehnertSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0003-4598-4966
Jessie C JacobsenSchool of Biological Sciences, The University of Auckland, Auckland, New Zealand.ORCID https://orcid.org/0000-0003-4426-2224

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Autism is a relatively common neurodevelopmental difference with considerable phenotypic heterogeneity impacting cognitive, sensory, and social processing, and often co-occurs with other conditions. Therefore, there is not a one-size-fits-all clinical support pathway for autistic individuals following diagnosis. DNA sequencing technology has enabled the discovery of genes causative of, or associated with, autism. Unsurprisingly, genetic heterogeneity goes hand-in-hand with the phenotypic heterogeneity for this condition; with causative genetic variation ranging from single base pair changes to complex chromosomal rearrangements in more than 100 different genes. This study captures a snapshot (201 individuals) of the autistic population (both clinically referred and self-referred) in Aotearoa New Zealand and documents a decade's research effort to refine diagnosis using a flexible and customised genome-wide sequencing approach. The diagnostic yield in this phenotypically disparate cohort was 12.9%, with an additional 15.9% of individuals harbouring 'likely causal' variants, providing the groundwork to tailor clinical, social, and educational care. Importantly, this study reveals the diagnostic utility of customised genetic screening for autism across a phenotypically diverse autistic population.

Indexed as

diagnostic yieldgenome-wide sequencingNeurodevelopmental conditionsself-referredwhole exome sequencingwhole genome sequencing

Identifiers

PMID40756852
PMCPMC12315138

What Socratic holds

Textmetadata
LicenceCC BY-NC-ND
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.