Evidence mapPaperPMID 40834345Full record

ArticleNeurology2025

Financial Toxicity and Its Determinants in Individuals Living With Inherited and Acquired Neuromuscular Disorders: The BIND Study.

Alyssa Grant, Ian C Smith, Lola E R Lessard, Homira Osman, Hanns Lochmuller, Hugh J McMillan, Gerald Pfeffer, Lawrence Korngut, Cynthia Gagnon, Stacey Lintern and 3 more

Abstract read
In one paragraph

Article in Neurology, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

0numbers the graph read from it
0cells of the map it votes in
2citing papers in PubMed
field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

2 citing papers in PubMed.

  1. Article
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4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

13 authors.

Alyssa GrantThe Ottawa Hospital Research Institute, Ontario, Canada.
Ian C SmithThe Ottawa Hospital Research Institute, Ontario, Canada.ORCID 0000-0001-5269-1710
Lola E R LessardUniversité Claude Bernard Lyon Est, Lyon, France.ORCID 0000-0002-3141-0227
Homira OsmanMuscular Dystrophy Canada, Toronto, Ontario, Canada.
Hanns LochmullerThe Ottawa Hospital Research Institute, Ontario, Canada.ORCID 0000-0003-2324-8001
Hugh J McMillanFaculty of Medicine, University of Ottawa, Ontario, Canada.ORCID 0000-0001-8927-2018
Gerald PfefferHotchkiss Brain Institute, Department of Clinical Neurosciences, Cumming School of Medicine, University of Calgary, Alberta, Canada.ORCID 0000-0002-7657-7098
Lawrence KorngutHotchkiss Brain Institute, Department of Clinical Neurosciences, Cumming School of Medicine, University of Calgary, Alberta, Canada.
Cynthia GagnonUniversity of Sherbrooke, Quebec, Canada.ORCID 0000-0003-2829-8470
Stacey LinternMuscular Dystrophy Canada, Toronto, Ontario, Canada.
Kathryn A SelbyBritish Columbia Children's Hospital, Vancouver, British Columbia, Canada; and.ORCID 0000-0001-9239-1704
Kednapa ThavornThe Ottawa Hospital Research Institute, Ontario, Canada.
Jodi Warman-ChardonThe Ottawa Hospital Research Institute, Ontario, Canada.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

BACKGROUND AND

objectivesIndividuals living with neuromuscular disease (NMD) often face substantial financial strain due to the chronic and progressive nature of these conditions. Despite growing awareness, the extent and determinants of financial toxicity (FT) in this population remain poorly understood. We assessed FT among individuals with NMD or their caregivers in Canada using a validated patient-reported outcome measure.

methodsWe conducted a national, cross-sectional survey of individuals with NMD or their caregivers registered with Muscular Dystrophy Canada (MDC). The survey, available in English and French, was completed online or by telephone with assistance from MDC personnel. FT was measured using the validated Comprehensive Score for Financial Toxicity (COST)-Functional Assessment of Chronic Illness Therapy questionnaire. Multivariable generalized linear models were used to identify factors associated with FT.

resultsA total of 1,426 participants (mean [SD] age, 52.0 [19.5] years; 52% female) completed the survey. Seventy-five percent reported household incomes below the national median, primarily because of reduced employment. The average COST score was 17.2 [10.4], significantly lower than scores reported in other chronic conditions, including cancer. Moreover, 70% of respondents had COST scores below 26, indicating moderate or severe FT. After adjusting for other factors, COST scores were significantly worse among caregivers than in adults with NMDs. Lower scores were also observed among individuals identified as racialized minority (rate ratio [RR] 0.74; 95% CI 0.64-0.87); those with lower household income (RR 0.59; 95% CI 0.51-0.69), those with lower education (RR 0.91; 95% CI 0.82-1.00), and those unable to work (RR 0.74; 95% CI 0.64-0.86); students (RR 0.54; 95% CI 0.34-0.86); or early retirees (RR 0.86, 95% CI 0.74-0.99). FT was also greater among those diagnosed with autoimmune myopathies (RR 0.82; 95% CI 0.73-0.92), spinal muscular atrophy (RR 0.79; 95% CI 0.66-0.96), and limb-girdle muscular dystrophy (RR 0.87; 95% CI 0.77-0.99). DISCUSSION: FT is highly prevalent among people living with NMDs, particularly caregivers and those with socioeconomic and clinical vulnerabilities. Policies to improve financial support and health care coverage for NMD-related needs could help alleviate this burden. Further research is required to understand the mechanisms contributing to FT within NMD subgroups.

Indexed as

Cost of IllnessFinancial StressNeuromuscular DiseasesAdultAgedCanadaCaregiversCross-Sectional StudiesFemaleHumansMaleMiddle AgedMuscular DystrophiesSurveys and QuestionnairesYoung Adult

Identifiers

PMID40834345
PMCPMC12367421

What Socratic holds

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LicenceCC BY-NC-ND
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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.