Evidence map›Paper›PMID 40993721›Full record

SynthesisOrphanet journal of rare diseases2025

Zebrafish models for congenital disorders of glycosylation (CDG): a systematic review.

N Gandoy-Fieiras, M I Quiroga, L Sánchez

Abstract readSystematic Review
In one paragraph

Synthesis in Orphanet journal of rare diseases, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

3 authors.

N Gandoy-FieirasDepartment of Zoology, Genetics and Physical Anthropology, Faculty of Veterinary, Universidade de Santiago de Compostela, Lugo, 27002, Spain. nerea.gandoy@usc.es.ORCID http://orcid.org/0000-0002-1762-6777
M I QuirogaDepartment of Anatomy, Animal Production and Veterinary Clinical Sciences, Faculty of Veterinary, Universidade de Santiago de Compostela, Lugo, 27002, Spain.
L SánchezDepartment of Zoology, Genetics and Physical Anthropology, Faculty of Veterinary, Universidade de Santiago de Compostela, Lugo, 27002, Spain.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Glycosylation is a post-translational modification of proteins that involves the addition of glycan groups and is essential for their proper functionality. This highly complex process affects 70% of all human proteins. Mutations in genes involved in glycosylation pathways can lead to a group of rare genetic syndromes known as Congenital Disorders of Glycosylation (CDG). One of the workflows applied to study human diseases includes animal models, such as the zebrafish. This systematic review aims to explore the utility of the zebrafish model in studying congenital disorders of glycosylation. For this purpose, searches were conducted in PubMed, Web of Science, and Scopus using terms related to congenital disorders of glycosylation and zebrafish, covering studies published up to November 2024. A total of 36 articles were identified based on the inclusion criteria. The results provide a comprehensive overview of these studies. The analysis reveals that CDGs related to N-glycosylation are the most frequently studied, morpholinos are the predominant technique used, zebrafish glycosylation genes exhibit a high degree of homology with human genes, and zebrafish models successfully replicate many of the clinical features observed in human CDG patients. This review highlights that zebrafish is a valuable strategy for studying CDG, offering important insights into the pathophysiology of these disorders and contributing to the development of potential therapeutic approaches.

Indexed as

Congenital Disorders of GlycosylationZebrafishAnimalsDisease Models, AnimalGlycosylationHumansAnimal modelCDGCongenital disorder of glycosylationDisease modelGlycosylationZebrafish

Identifiers

PMID40993721
PMCPMC12462111

What Socratic holds

Textmetadata
LicenceCC BY
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Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.