Evidence map›Paper›PMID 41118103›Full record

ArticleJournal of assisted reproduction and genetics2025

Genetic analyses using chromosomal microarray and exome sequencing in fetuses and women with Müllerian duct anomalies.

Auriane Cospain, Paul Rollier, Anna Lokchine, Erika Launay, Ludivine Dion, Alinoé Lavillaureix, Godelieve Morel, Laura Mary, Laurent Pasquier, Chloé Quelin and 14 more

Abstract read
In one paragraph

Article in Journal of assisted reproduction and genetics, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

24 authors.

Auriane CospainUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France. auriane.cospain@chu-rennes.fr.ORCID http://orcid.org/0000-0002-0007-4195
Paul RollierUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Anna LokchineUniv Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France.
Erika LaunayUniv Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France.
Ludivine DionUniv Rennes, Inserm, EHESP, Irset (Institut de Recherche en Santé, environnement et travail), UMR S 1085, Rennes, France.
Alinoé LavillaureixUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Godelieve MorelUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Laura MaryUniv Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France.
Laurent PasquierUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Chloé QuelinUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Fabrice G PetitUniv Rennes, Inserm, EHESP, Irset (Institut de Recherche en Santé, environnement et travail), UMR S 1085, Rennes, France.
Soazik P JaminUniv Rennes, Inserm, EHESP, Irset (Institut de Recherche en Santé, environnement et travail), UMR S 1085, Rennes, France.
Mélanie FradinUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Bénédicte NouyouUniv Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France.
Wilfrid CarréUniv Rennes, CHU Rennes (Service de Génétique Moléculaire Et Génomique), Rennes, France.
Régis BouvetUniv Rennes, CHU Rennes (Service de Génétique Moléculaire Et Génomique), Rennes, France.
Lenaick Detivaud GauthierUniv Rennes, CHU Rennes (Service de Génétique Moléculaire Et Génomique), Rennes, France.
Daniel GuerrierUniv Rennes, CNRS, INSERM, IGDR (Institut de Génétique Et Développement de Rennes), UMR 6290, ERL U1305, Rennes, France.
Marie FaoucherUniv Rennes, CHU Rennes (Service de Génétique Moléculaire Et Génomique), Rennes, France.
Christèle DubourgUniv Rennes, CHU Rennes (Service de Génétique Moléculaire Et Génomique), Rennes, France.
Sylvie OdentUniv Rennes, CHU Rennes (Service de Génétique Clinique, CLAD Ouest, FHU GenOMedS), Rennes, France.
Marc-Antoine Belaud RotureauUniv Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France.
Vincent Lavoue *Univ Rennes, Inserm, EHESP, Irset (Institut de Recherche en Santé, environnement et travail), UMR S 1085, Rennes, France.
Sylvie Jaillard *Univ Rennes, CHU Rennes (Laboratoire de Cytogénétique Et Biologie Cellulaire), Rennes, France. sylvie.jaillard@chu-rennes.fr.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

purposeThis study aims to explore the genetic anomalies (excluding aneuploidy) associated with Müllerian duct anomalies (MDA). This project is part of a large uterine transplantation (UTx) program, where women with MRKH (Mayer-Rokitansky-Küster-Hauser) syndrome are the primary candidates. The potential of the hereditary nature of MDA was evaluated to facilitate appropriate genetic counseling when applicable.

methodsWe used chromosome microarray analysis (CMA) and exome sequencing (ES) to identify genetic variations that may contribute to the phenotype of MDA. A comprehensive description of the genital and extra-genital phenotype was established for each individual in whom a potentially relevant genetic variant has been identified.

resultsWe analyzed data from 3 fetuses and 75 women with MDA. All individuals had CMA and 65 ES were analyzed. CMA identified 6 copy number variations (CNVs) of interest (diagnostic yield: 7.7%), notably the recurrent 17q12 deletion. In 13.8% of individuals, ES revealed likely pathogenic or pathogenic variants that fully explained the phenotype in affected individuals, variants of uncertain significance (VUS) of interest in the pathology, or variants unrelated to MDA but linked to other symptoms presented by the individuals.

conclusionThe findings underscore the crucial role of genetics in understanding and managing MDA. With the emergence of UTx, assessing the risk of transmission and recurrence of genetic anomalies is essential. In addition, genetic analysis may enable early medical prevention for associated phenotypes. Genetic analysis is therefore becoming an essential component of the clinical assessment and counseling for women with MDA.

Indexed as

46, XX Disorders of Sex DevelopmentDisorder of Sex Development, 46,XYMullerian DuctsAdultCongenital AbnormalitiesDNA Copy Number VariationsExome SequencingFemaleFetusGenetic TestingHumansMicroarray AnalysisPhenotypePregnancyExome sequencingGREB1LMicrodeletion 17q12MRKHMüllerian duct anomaly

Identifiers

PMID41118103
PMCPMC12705522

What Socratic holds

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.