Evidence map›Paper›PMID 41549766›Full record

ArticleJournal of the peripheral nervous system : JPNS2026

Broadening the Clinical Spectrum of Axonal Hereditary Neuropathies: A Comparative Case Study on DNAJB2- and HINT1-Related Disease.

Bogdan Bjelica, Corinna Hendrich, Sandra von Hardenberg, Milica Vukojevic, Sonja Körner, Thomas Gschwendtberger, Aiden Haghikia, Stojan Peric, Susanne Petri

Abstract readComparative Study
In one paragraph

Article in Journal of the peripheral nervous system : JPNS, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

9 authors.

Bogdan BjelicaDepartment of Neurology, Hannover Medical School, Hannover, Germany.ORCID https://orcid.org/0000-0002-1783-703X
Corinna HendrichDepartment of Human Genetics, Hannover Medical School, Hannover, Germany.
Sandra von HardenbergDepartment of Human Genetics, Hannover Medical School, Hannover, Germany.
Milica VukojevicNeurology Clinic, University Clinical Center of Serbia, Faculty of Medicine, University of Belgrade, Belgrade, Serbia.
Sonja KörnerDepartment of Neurology, Hannover Medical School, Hannover, Germany.
Thomas GschwendtbergerDepartment of Neurology, Hannover Medical School, Hannover, Germany.
Aiden HaghikiaDepartment of Neurology, Hannover Medical School, Hannover, Germany.
Stojan PericNeurology Clinic, University Clinical Center of Serbia, Faculty of Medicine, University of Belgrade, Belgrade, Serbia.ORCID https://orcid.org/0000-0002-2979-556X
Susanne PetriDepartment of Neurology, Hannover Medical School, Hannover, Germany.

Funding

Deutsche Forschungsgemeinschaft DFG ME 3696/3Hannover Medical School
6 · The paper itself

Abstract

BACKGROUND AND

aimsDifferentiating hereditary axonal polyneuropathies caused by distinct gene variants remains a clinical challenge. This comparative case study of DNAJB2- and HINT1-related neuropathies aimed to broaden the phenotypic spectrum associated with these genes and to explore non-motor symptoms and quality of life (QoL) in affected individuals.

methodsSix patients carrying two novel DNAJB2 variants and six age-matched patients with HINT1 variants underwent detailed clinical and electrophysiological characterization. Motor function was assessed longitudinally using the Medical Research Council (MRC) scale. Non-motor symptoms (neuropathic pain, autonomic dysfunction, depression, fatigue, restless legs syndrome) and QoL were evaluated with patient-reported outcomes and compared to four healthy controls (HC).

resultsBoth patient groups exhibited a CMT2 phenotype. Nerve conduction studies revealed a length-dependent axonal predominantly motor but not pure motor neuropathy in most of the patients. Disease onset tended to occur later in patients with DNAJB2 variants, who yet developed more severe neuropathy. The spectrum of additional clinical features differed between the two groups. All patients with DNAJB2 variants fulfilled criteria for depression, compared with one with a HINT1 variant. Significant fatigue was present in the majority of both groups, while restless legs syndrome was observed in four patients with a DNAJB2 variant but in none with a HINT1. QoL was significantly reduced in DNAJB2 versus HC, with no difference in QoL between patients with DNAJB2 and HINT1 variants.

interpretationThis study expands the clinical spectrum of DNAJB2- and HINT1-related neuropathies, highlighting distinct non-motor features and their impact on QoL, and providing the first direct comparison of these two rare axonal disorders.

Indexed as

Charcot-Marie-Tooth DiseaseHSP40 Heat-Shock ProteinsMolecular ChaperonesNerve Tissue ProteinsAdultAgedFemaleHumansMaleMiddle AgedQuality of LifeDNAJB2 protein, humanHINT1 protein, humanHSP40 Heat-Shock ProteinsMolecular ChaperonesNerve Tissue ProteinsDNAJB2 neuropathyhereditary axonal neuropathyHINT1 neuropathynon‐motor symptomsquality of life

Identifiers

PMID41549766
PMCPMC12813656

What Socratic holds

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LicenceCC BY
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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.