Evidence mapPaperPMID 41787606Full record

ArticleMovement disorders : official journal of the Movement Disorder Society2026

An Open-Label Phase 1b Study of the Safety, Pharmacokinetics, Pharmacodynamics, and Clinical Activity of ANX005 in Patients with Huntington's Disease.

Rajeev Kumar, Pinky Agarwal, Karen Anderson, Daniel Claassen, Marissa Dean, Andrew Duker, Burton Scott, Benjamin Hoehn, Ann Mongan, Ping Lin and 6 more

Registry-linked trialAbstract readMulticenter StudyClinical Trial, Phase I
In one paragraph

Article in Movement disorders : official journal of the Movement Disorder Society, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. It is linked to trial NCT04514367 (A Phase 2a Open Label Study to Assess the Safety, Tolerability, Pharmacokinetics and Pharmacodynamics of Intravenous ANX005 in Subjects With, or at Risk for, Manifest Huntington's Disease), which is not on this map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

NCT04514367 phase2completednot on this map

A Phase 2a Open Label Study to Assess the Safety, Tolerability, Pharmacokinetics and Pharmacodynamics of Intravenous ANX005 in Subjects With, or at Risk for, Manifest Huntington's Disease

TypeinterventionalSponsorAnnexon, Inc.Ran2020 to 2022Enrolled28ConditionsHuntington DiseaseArmsANX005
3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

16 authors.

Rajeev KumarRocky Mountain Movement Disorders Center, Englewood, Colorado, USA.
Pinky AgarwalEvergreen Healthcare, Kirkland, Washington, USA.
Karen AndersonGeorgetown University, Washington, DC, USA.
Daniel ClaassenVanderbilt University Medical Center, Nashville, Tennessee, USA.
Marissa DeanUniversity of Alabama at Birmingham, Birmingham, Alabama, USA.
Andrew DukerUC Gardner Neuroscience Institute, Cincinnati, Ohio, USA.
Burton ScottDuke University, Durham, North Carolina, USA.
Benjamin HoehnAnnexon Biosciences, Brisbane, California, USA.
Ann MonganAnnexon Biosciences, Brisbane, California, USA.
Ping LinAnnexon Biosciences, Brisbane, California, USA.
Ellen Cahir-McFarlandAnnexon Biosciences, Brisbane, California, USA.
Lori TaylorAnnexon Biosciences, Brisbane, California, USA.
Glenn MorrisonAnnexon Biosciences, Brisbane, California, USA.
Ted YednockAnnexon Biosciences, Brisbane, California, USA.
Sanjay KeswaniAnnexon Biosciences, Brisbane, California, USA.
Henk-Andre KroonAnnexon Biosciences, Brisbane, California, USA.

Funding

Annexon Biosciences
6 · The paper itself

Abstract

backgroundThe classical complement pathway is implicated in the progression of neurodegenerative disease through its ability to drive aberrant removal of synapses, neuroinflammation, and neuronal damage. ANX005 is a humanized monoclonal antibody targeting C1q that blocks classical complement pathway activation.

objectiveThe aim was to assess the safety, pharmacokinetics (PK), pharmacodynamics, and clinical activity of ANX005 in patients with Huntington's disease (HD).

methodsANX005-HD-01 (NCT04514367) was a multicenter, open-label, phase 1b study in patients with early-manifest HD. Primary endpoints included safety, tolerability, PK, and complement C1q and C4a/C4 levels in the serum and cerebrospinal fluid (CSF). Exploratory clinical activity endpoints included changes from baseline in composite Unified Huntington's Disease Rating Scale (cUHDRS) and component scores.

resultsAll patients who received study drug (n = 28) experienced ≥1 treatment-emergent adverse event, mostly transient infusion-related reactions on the first dose. Three patients with elevated baseline antinuclear antibodies withdrew from the study due to treatment-related AEs (pneumonitis) or serious AEs (systemic lupus erythematous, hemolysis). Twenty-three patients (82.1%) received all planned ANX005 infusions. Steady-state PK was achieved by week 6, with full saturation of ANX005 observed in serum and the CSF. Stabilization or possible improvement in cUHDRS and total functional capacity through 36 weeks was observed in a patient subgroup with higher baseline complement activity, based on baseline C4a/C4 ratio in CSF.

conclusionOverall, AEs with ANX005 administration were manageable, and most patients received all planned doses. Evidence of clinical improvement with ANX005 was observed in patients with higher baseline complement activity, supporting future study in patients with HD. © 2026 The Author(s). Movement Disorders published by Wiley Periodicals LLC on behalf of International Parkinson and Movement Disorder Society.

Indexed as

Antibodies, Monoclonal, HumanizedComplement C1qHuntington DiseaseAdultFemaleHumansMaleMiddle AgedTreatment OutcomeAntibodies, Monoclonal, HumanizedComplement C1qANX005C1qclassical complement cascadeclinical trialHuntington's disease

Identifiers

PMID41787606
PMCPMC13307253

What Socratic holds

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Registered trials

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.