Evidence map›Paper›PMID 42410653›Full record

SynthesisMolecular genetics & genomic medicine2026

COQ2-Associated Primary Coenzyme Q10 Deficiency Presenting With Proteinuria: A Case Report and Literature Review.

Yuqi Yue, Fei Zhao, Qiuxia Chen

Abstract readCase ReportsSystematic Review
In one paragraph

Synthesis in Molecular genetics & genomic medicine, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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1 · What the graph read from it

What it found

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2 · The registry

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3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

3 authors.

Yuqi YueDepartment of Nephrology, Children's Hospital of Nanjing Medical University, Nanjing, China.ORCID https://orcid.org/0009-0006-7450-0907
Fei ZhaoDepartment of Nephrology, Children's Hospital of Nanjing Medical University, Nanjing, China.
Qiuxia ChenDepartment of Nephrology, Children's Hospital of Nanjing Medical University, Nanjing, China.

Funding

Nanjing Special Fund for Health Science and Technology Development ZKX21046
6 · The paper itself

Abstract

backgroundPrimary coenzyme Q10 (CoQ10) deficiency (PCOQ10D) is an autosomal recessive mitochondrial disorder caused by pathogenic variants in genes involved in the CoQ10 biosynthetic pathway, including PDSS2, COQ2, COQ6, and COQ8B/ADCK4. Among these, pathogenic variants in the COQ2 gene impair oxidative phosphorylation and mitochondrial biogenesis in podocytes, often leading to encephalopathy and nephropathy.

methodsClinical data were collected from a pediatric patient with proteinuria caused by COQ2 gene variants, who was admitted to the Children's Hospital Affiliated to Nanjing Medical University in June 2025. Relevant examinations were completed, and whole-exome sequencing (WES) was performed to screen for potential genetic variants in the patient's genomic DNA. Pathogenicity assessment of the identified variants was conducted in accordance with the American College of Medical Genetics and Genomics (ACMG) guidelines and online bioinformatics tools. Additionally, a systematic literature review on COQ2-associated nephropathy was carried out in this study.

resultsThe patient initially presented with global developmental delay accompanied by neurological lesions and developed proteinuria at 6 months of age. Genetic testing revealed two pathogenic variants: c.368G>A, p.(Arg123His) and c.908A>G, p.(Tyr303Cys). After oral administration of high-dose CoQ10 (85 mg/kg/d) combined with enalapril maleate (0.80 mL/kg/d), the patient achieved complete remission of proteinuria and maintained stable renal function.

conclusionsPCOQ10D exhibits marked phenotypic heterogeneity, characterized by variations in age of onset, organ involvement, and clinical severity, as well as significant interindividual differences in treatment responses to CoQ10 supplementation. This case expands the phenotypic spectrum of the disease. Moreover, the therapeutic outcomes suggest that all diagnosed patients require long-term supplementation with adequate doses of CoQ10, which is of great significance for delaying disease progression.

Indexed as

Alkyl and Aryl TransferasesAtaxiaMitochondrial DiseasesMuscle WeaknessProteinuriaUbiquinoneFemaleHumansInfant4-hydroxybenzoate polyprenyltransferaseAlkyl and Aryl Transferasescoenzyme Q10UbiquinoneCOQ2 geneprimary coenzyme Q10 deficiency‐1proteinuria

Identifiers

PMID42410653
PMCPMC13337543

What Socratic holds

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the Socratic graph.